我們報導一位五十八歲女性，因左側腎囊腫接受超音波導引抽水及95％酒精硬化治療，病人於2星期後出現明顯血尿，左側逆行性腎盂攝影發現左腎囊腫約8公分大小，且與集尿系統有相連通，因血尿症狀持續，故安排手術將左腎囊腫切除、術中發現左腎有三個囊腫並以可彎式輸尿管鏡檢查，其中二個囊腫確實和集尿糸統問有通道、手術並將連接處縫合；術後恢復情形良好，三個月後超音波檢查只剩l公分大小之囊腫。本病例之明顯血尿及左側腎囊腫與集尿系統有相連通情形，據推斷可能是原本囊腫和腎盂即有相連通的情形，從未在文獻上被報告過，我們將於本文中介紹此病例的臨床上特徵及處理方式。

A 57-year-old female suffered from left flank pain for several weeks. Bilateral renal cysts were diagnosed by ultrasonography of the kidney. Sono-guided aspiration and ethanol sclerotherapy were performed for the left renal cyst. Painless gross hematuria was found 14 days later. Retrograde pyelography revealed that the renal cyst communicated with the left collecting system. Un-roofing of the left renal cysts was performed and multiple simple renal cysts communicating with the left collecting system were also noted. To our knowledge, no such case has been reported in the English literature. We also describe the clinical features and management of this disease.